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Record W4416098852 · doi:10.1093/neuonc/noaf264

A systematic study of molecular diagnosis, treatment, and prognosis in infant-type hemispheric glioma: An individual patient data meta-analysis of 164 patients

2025· article· en· W4416098852 on OpenAlexaff
Lara Chavaz, Aditi Bagchi, Sandeep Kumar Dhanda, Fabienne Toutain, Stefan M. Pfister, Dominik Sturm, Torsten Pietsch, Gerrit H. Gielen, Andreas Waha, Matthew Clarke, Congyu Lu, Michael Karremann, Martin Benesch, Thomas Perwein, Gunther Nussbaumer, Christof M. Kramm, Maura Massimino, Veronica Biassoni, Maria Vinci, Angela Mastronuzzi, Dannis G. van Vuurden, Sophie E. M. Veldhuijzen van Zanten, Alan Mackay, Chris Jones, David Jones, Ana Guerreiro Stücklin, Uri Tabori, Cynthia Hawkins, Scott Ryall, Andrés Morales La Madrid, Álvaro Lassaletta, Simon Bailey, Darren Hargrave, Jason Chiang, Moatasem El‐Ayadi, Bruna Minniti Mançano, Rui Manuel Reis, Christian Hagel, Hamza Gorsi, Nicolas Silvestrini, Ahmed Gilani, L. I. Papusha, Paul Klimo, Xin Zhou, Amar Gajjar, Giles Robinson, André O. von Bueren

Bibliographic record

VenueNeuro-Oncology · 2025
Typearticle
Languageen
FieldMedicine
TopicGlioma Diagnosis and Treatment
Canadian institutionsHospital for Sick Children
FundersNational Cancer InstituteNIHR Great Ormond Street Hospital Biomedical Research CentreNationales Centrum für Tumorerkrankungen HeidelbergGreat Ormond Street Institute of Child HealthUniversité de GenèveCRIS Cancer FoundationCancer Research UKDeutsches KrebsforschungszentrumSt. Jude Children's Research HospitalNew York State Department of HealthAmerican Lebanese Syrian Associated CharitiesNational Institute on Handicapped Research
KeywordsPatient dataFocus (optics)Patient carePrimary careMEDLINEDisease

Abstract

fetched live from OpenAlex

BACKGROUND: Due to the novelty and rarity of infant-type hemispheric glioma (IHG), optimal treatment and factors determining clinical outcomes are yet to be established. METHODS: We curated a series of 164 patients with IHG; 155 identified by methodical literature search and nine additional patients contributed by collaborators. RESULTS: All tumors were hemispheric, diagnosed at a median age of 3.4 (0-52) months, and frequently (95%) non-metastatic. One hundred forty-two (86.5%) tumors harbored fusions involving receptor tyrosine kinase (RTK) genes (ALK [67/142, 47%], NTRK1/2/3 [32/142, 22.5%], ROS1 [29/142, 20.4%], MET [13/142, 9.2%], and ABL2 [1/142, 0.7%]). Sixty-four percentage, 20%, and 8% of patients were treated with surgery and adjuvant chemotherapy, surgery-only, and surgery plus targeted therapy, respectively. Five patients received radiation. Three-year event-free survival (EFS) and overall survival (OS) was 49.5% [40.7-60.2] and 79.6% [72.1-87.9], respectively. Twenty-two patients succumbed to disease, of which tumor progression (8/22, 36%) and intra-cranial hemorrhage (5/22, 23%) were the most common causes. Multivariate analysis showed that the factors most associated with an increased risk of death were no treatment except for surgery and presence of residual tumor after definitive surgery. These findings present a challenging dichotomy where surgery is both a serious risk factor for early death and, when successful, a benefit. CONCLUSIONS: Together, these findings show that IHG is a fusion driven tumor of the very young that is survivable even after progression. While optimal primary therapy for patients with IHG has yet to be established, the findings of this meta-analysis suggest treatment should focus on lowering surgical morbidity and improving its success.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame machine prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. The Gemma side is a direct model label for every work in the frame, read from the title-only record. The Codex side is a classifier learned from the 10,348 direct Codex labels and calibrated to design-weighted sample rates; fields without enough sample support carry no Codex call. Candidate is the union of the two sides; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels.

metaresearch head score (Codex)0.008
metaresearch head score (Gemma)0.012
Version: metacan-v3-hybrid-931329e0061cValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Meta-analysis · Consensus signal: Meta-analysis
GenreCandidate signal: Empirical · Consensus signal: none
Teacher disagreement score0.008
Threshold uncertainty score0.040

Distilled classifier scores by category (both heads)

CategoryCodexGemma
Metaresearch0.0080.012
Meta-epidemiology (narrow)0.0010.001
Meta-epidemiology (broad)0.0070.021
Bibliometrics0.0030.005
Science and technology studies0.0010.000
Scholarly communication0.0020.001
Open science0.0010.001
Research integrity0.0010.001
Insufficient payload (model declined to judge)0.0020.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.066
GPT teacher head0.351
Teacher spread0.285 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one source (direct Gemma or distilled Codex), not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designMeta-analysis
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations0
Published2025
Admission routes1
Has abstractyes

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