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Record W4416552407 · doi:10.1186/s13287-025-04781-w

Cutting-edge treatments in amyotrophic lateral sclerosis: the role of molecular pathogenesis in targeted therapies

2025· article· en· W4416552407 on OpenAlexaff
Ramin Raoufinia, Ghazal Alyari, Amin Tadayoni Nia, Mohammad Reza Abbaszadegan, Ali Mahmoudi, Sajjad Shafaeibajestan, Ehsan Saburi, Jalil Tavakol‐Afshari, Faezeh Jamali, S H Salari, Amir Reza Boroumand, Hamid Reza Rahimi

Bibliographic record

VenueStem Cell Research & Therapy · 2025
Typearticle
Languageen
FieldMedicine
TopicAmyotrophic Lateral Sclerosis Research
Canadian institutionsCapital District Health Authority
Fundersnot available
KeywordsAmyotrophic lateral sclerosisRiluzoleNeuroinflammationDiseaseNeurotrophic factorsSOD1Spinal muscular atrophyStem cell

Abstract

fetched live from OpenAlex

Amyotrophic lateral sclerosis (ALS) is a devastating neurodegenerative disorder characterized by the selective loss of motor neurons (MNs), leading to progressive muscle weakness, atrophy, and ultimately paralysis. This review provides a comprehensive overview of the molecular mechanisms underlying ALS pathogenesis, the genetic mutations associated with both familial and sporadic forms of the disease, and the latest therapeutic strategies aimed at mitigating disease progression. mutations in genes such as C9orf72, SOD1, TARDBP, and FUS have been implicated in ALS, with an intricate interplay of protein misfolding, oxidative stress, mitochondrial dysfunction, excitotoxicity, and neuroinflammation contributing to motor neuron degeneration. While current FDA-approved treatments such as Riluzole and Edaravone offer only modest benefits and do not significantly halt disease progression. Emerging therapies, including gene therapies (e.g., antisense oligonucleotides (ASOs) and CRISPR/Cas9, stem cell-based approaches, and neurotrophic factor supplementation, are demonstrating promising results in preclinical and early-phase clinical trials. novel approaches aim to target, modulate, and promote regeneration, renewed hope for future ALS treatments. However, several challenges remain, including effective delivery methods, safety concerns, and the inherent complexity of ALS pathology, ongoing research continues to explore these innovative interventions with the goal of improving clinical outcomes for patients. This review highlights the importance of personalized therapeutic approaches and underscores the necessity of continued innovation in ALS research, with the ultimate goal of developing disease-modifying therapies and, potentially, a cure for this fatal condition. Amyotrophic Lateral Sclerosis, Neurodegenerative Diseases, C9orf72 Mutation, SOD1 Mutation, Riluzole This comprehensive review article presents an in-depth analysis of the molecular pathogenesis of Amyotrophic Lateral Sclerosis (ALS), emphasizing the complex interplay of genetic mutations, protein misfolding, oxidative stress, mitochondrial dysfunction, excitotoxicity, and neuroinflammation that collectively drive motor neuron degeneration. By systematically categorizing ALS subtypes based on genetic, clinical, and molecular characteristics, the article elucidates the diverse mechanisms underlying both familial and sporadic forms of the disease. Notably, it highlights key genetic mutations such as those in C9orf72, SOD1, TARDBP, and FUS and details how these contribute to disease pathology through distinct molecular pathways. The review integrates recent advances in understanding ALS heterogeneity and the impact of gene-environment interactions and epigenetic factors, underscoring the necessity for personalized therapeutic approaches. A novel aspect of this review is its comprehensive coverage of cutting-edge therapeutic strategies targeting ALS at the molecular level, including gene therapies like antisense oligonucleotides (ASOs), RNA interference, and CRISPR/Cas9 gene editing, alongside stem cell-based treatments and antibody-mediated interventions. The article critically evaluates the current state of FDA-approved drugs, such as Riluzole and Edaravone, noting their limited efficacy, while bringing to light promising preclinical and clinical trial data on novel treatments aimed at halting or reversing disease progression. Furthermore, it discusses the challenges inherent in delivering therapies across the blood-brain barrier, safety concerns, and the need for robust clinical trial designs. By integrating molecular insights with therapeutic innovations and clinical perspectives, this review advances the field by providing a valuable roadmap for future research focused on developing effective, disease-modifying treatments for ALS.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame machine prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. The Gemma side is a direct model label for every work in the frame, read from the title-only record. The Codex side is a classifier learned from the 10,348 direct Codex labels and calibrated to design-weighted sample rates; fields without enough sample support carry no Codex call. Candidate is the union of the two sides; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels.

metaresearch head score (Codex)0.002
metaresearch head score (Gemma)0.001
Version: metacan-v3-hybrid-931329e0061cValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Not applicable · Consensus signal: none
GenreCandidate signal: Review · Consensus signal: Review
Teacher disagreement score0.003
Threshold uncertainty score0.010

Distilled classifier scores by category (both heads)

CategoryCodexGemma
Metaresearch0.0020.001
Meta-epidemiology (narrow)0.0010.000
Meta-epidemiology (broad)0.0010.001
Bibliometrics0.0010.001
Science and technology studies0.0000.001
Scholarly communication0.0020.002
Open science0.0010.001
Research integrity0.0020.003
Insufficient payload (model declined to judge)0.0030.001

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.046
GPT teacher head0.329
Teacher spread0.283 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one source (direct Gemma or distilled Codex), not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designNot applicable
Domainnot available
GenreReview

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations1
Published2025
Admission routes1
Has abstractyes

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