MétaCan
Menu
Back to cohort
Record W4416605431 · doi:10.1186/s13063-025-09291-x

Who benefits? Uncovering hidden heterogeneity of treatment effects in adaptive trials using Bayesian methods: a systematic review

2025· article· en· W4416605431 on OpenAlexafffund
Rachel Giblon, Kuan Liu, Yongdong Ouyang, Jessie Cunningham, Allen L. Pimienta, Ewan C. Goligher, Anna Heath

Bibliographic record

VenueTrials · 2025
Typearticle
Languageen
FieldMathematics
TopicStatistical Methods in Clinical Trials
Canadian institutionsUniversity Health NetworkUniversity of TorontoSickKids FoundationInstitute for Clinical Evaluative SciencesPublic Health OntarioHospital for Sick Children
FundersNatural Sciences and Engineering Research Council of CanadaGroupe canadien de recherche en soins intensifsNational Sanitarium Association
KeywordsBayesian probabilityClinical trialEquity (law)Bayes' theoremBayesian statisticsMEDLINEResearch designBayesian inference

Abstract

fetched live from OpenAlex

BACKGROUND: Adaptive clinical trials increasingly aim to detect heterogeneity of treatment effect (HTE) to guide personalized care. However, most adaptive designs rely on predefined subgroups and are limited in their ability to uncover unknown or complex sources of HTE. Bayesian statistical methods offer a flexible alternative, enabling real-time learning and adaptation within trials. This review evaluates Bayesian methods used to detect hidden HTE in adaptive clinical trials, with attention to their methodological innovations, operating characteristics, and consideration of equity and inclusion in trial design. METHODS: We conducted a systematic search of MEDLINE, Embase, and other databases to identify original studies that developed Bayesian methods for detecting unknown HTE within adaptive clinical trial designs. Eligible studies were reviewed and synthesized based on design features, statistical methodology, operating characteristics, reproducibility, and whether equity-related factors were explicitly considered. Equity considerations included whether studies incorporated variables related to underrepresented populations-such as age, sex, race/ethnicity, or geography-examined intersectional subgroup effects, or explicitly framed their methods as tools to address health disparities. RESULTS: Of 2826 screened records, seven studies met inclusion criteria. Bayesian methods included random partition models, spatial models, logistic regression with dimension reduction, adaptive randomization using machine learning classifiers, and adaptive enrichment or platform designs incorporating model averaging or latent subgroup estimation. In simulation studies, these methods often showed improvements in subgroup detection, efficiency, or power relative to non-Bayesian comparators. None were tested using real-world trial data. Reproducibility was limited overall, with analytic code only available for the three most recent studies. Notably, none explicitly framed their methods as tools to address inequities in treatment outcomes across population subgroups. CONCLUSIONS: The small number of simulation-based studies illustrates preliminary but promising directions for applying Bayesian methods to detect HTE in adaptive clinical trials. While these approaches demonstrate potential to enhance trial adaptability, scalability, and inclusiveness, current evidence remains limited and largely conceptual. Incorporating an equity lens into future methodological development, alongside greater emphasis on empirical validation and open science practices, will be essential to determine their practical value in advancing equitable clinical research.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame distilled prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. Learned from the 10,348 direct Codex labels and 10,348 direct Gemma labels. Candidate is the union of thresholded teacher heads; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels or direct frontier model labels.

metaresearch head score (Codex)0.105
metaresearch head score (Gemma)0.693
Version: codex-gemma-dda1882f352aValidation status: machine_predicted_unvalidated
Candidate categoriesMetaresearch, Meta-epidemiology (narrow)
Consensus categoriesMetaresearch
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Systematic review · Consensus signal: none
GenreCandidate signal: Methods · Consensus signal: Methods
Teacher disagreement score0.588
Threshold uncertainty score1.000

Codex and Gemma teacher scores by category

CategoryCodexGemma
Metaresearch0.1050.693
Meta-epidemiology (narrow)0.0010.000
Meta-epidemiology (broad)0.0140.001
Bibliometrics0.0000.001
Science and technology studies0.0000.000
Scholarly communication0.0000.000
Open science0.0000.000
Research integrity0.0000.000
Insufficient payload (model declined to judge)0.0000.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.718
GPT teacher head0.639
Teacher spread0.079 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; both teacher heads agree on what is shown here.

Study designSystematic review
Domainnot available
GenreMethods

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations1
Published2025
Admission routes2
Has abstractyes

Explore more

Same venueTrialsSame topicStatistical Methods in Clinical TrialsFrench-language works237,207