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Record W4416910352 · doi:10.1016/j.cmi.2025.11.027

Comparing different methods for analysing hierarchical composite endpoints: two illustrative case studies with post hoc analyses of the BALANCE (Bacteraemia Antibiotic Length Actually Needed for Clinical Effectiveness) and CAMERA2 (Combination Antibiotics for methicillin-resistant Staphylococcus aureus) randomized clinical trials

2025· article· en· W4416910352 on OpenAlexafffund
Sean Wei Xiang Ong, Ruxandra Pinto, Robert K. Mahar, Neta Petersiel, Robert Fowler, Joshua S. Davis, Nick Daneman, Steven Y. C. Tong

Bibliographic record

VenueClinical Microbiology and Infection · 2025
Typearticle
Languageen
FieldMathematics
TopicStatistical Methods in Clinical Trials
Canadian institutionsHealth Sciences CentreUniversity of TorontoSunnybrook Health Science Centre
FundersHealth Research Council of New ZealandNational Health and Medical Research CouncilCanadian Institutes of Health ResearchUniversity of MelbourneUniversity of TorontoNational Medical Research CouncilOntario Ministry of Health and Long-Term Care
KeywordsPost hocBalance (ability)AntibioticsPost-hoc analysisAntibacterial agent

Abstract

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OBJECTIVES: Hierarchical composite endpoints (HCEs) are increasingly being used in infectious disease research. In this paper, we illustrate different methods for analysing HCEs in post hoc analyses of the Bacteraemia Antibiotic Length Actually Needed for Clinical Effectiveness (BALANCE) and Combination Antibiotics for MEthicillin Resistant Staphylococcus aureus (CAMERA2) clinical trials. METHODS: We constructed post hoc HCEs for each trial by combining clinical efficacy and safety outcomes: (a) mortality, relapse of bacteraemia, and antibiotic adverse events for BALANCE, and (b) mortality, primary treatment failure, infectious complications, and antibiotic adverse events for CAMERA2. For both trials, we additionally included length of stay or duration of antibiotic treatment as tiebreakers after the primary HCE in separate analyses. We applied these analytic methods: (a) logistic regression using a binary composite outcome, (b) generalized pairwise comparisons using different outcome permutations, (c) Wilcoxon rank sum approach for an ordinal outcome, (d) proportional odds model, and (e) probabilistic index model. We estimated the probabilistic index, win ratio, win odds, net treatment benefit, or odds ratio where possible using each method. RESULTS: For the BALANCE trial, all analyses of the primary HCE resulted in the same conclusion of no evidence of differences between treatment groups. Inclusion of length of stay as a tiebreaker resulted in 7 of 11 analyses finding the 7-day treatment arm superior to the 14-day arm, whereas inclusion of antibiotic duration resulted in all analyses concluding superiority of the 7-day treatment arm. For the CAMERA2 trial, all analyses found no evidence of differences between the two treatment groups. For all analyses, there were only minor differences in estimates across different analytic methods. CONCLUSIONS: In these post hoc analyses, different methods for analysing HCEs resulted in similar effect estimates and conclusions consistent with the primary analyses of the BALANCE and CAMERA2 trials. These analyses illustrate how different HCEs can be constructed and analysed, and may be useful to other researchers in designing future studies that use HCEs.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame distilled prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. Learned from the 10,348 direct Codex labels and 10,348 direct Gemma labels. Candidate is the union of thresholded teacher heads; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels or direct frontier model labels.

metaresearch head score (Codex)0.084
metaresearch head score (Gemma)0.391
Version: codex-gemma-dda1882f352aValidation status: machine_predicted_unvalidated
Candidate categoriesMetaresearch, Meta-epidemiology (narrow), Science and technology studies
Consensus categoriesMetaresearch
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Randomized trial · Consensus signal: none
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.449
Threshold uncertainty score1.000

Codex and Gemma teacher scores by category

CategoryCodexGemma
Metaresearch0.0840.391
Meta-epidemiology (narrow)0.0010.000
Meta-epidemiology (broad)0.0070.002
Bibliometrics0.0000.000
Science and technology studies0.0010.004
Scholarly communication0.0000.000
Open science0.0000.000
Research integrity0.0010.001
Insufficient payload (model declined to judge)0.0000.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.493
GPT teacher head0.631
Teacher spread0.138 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; both teacher heads agree on what is shown here.

Study designRandomized trial
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations1
Published2025
Admission routes2
Has abstractyes

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