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Record W7135097939 · doi:10.1093/neuped/wuaf001.031

CP-03. Sex-associated differences in disease progression and functional outcomes of adamantinomatous craniopharyngioma in prepubescent patients

2025· article· en· W7135097939 on OpenAlex
Yang Zhou, Eric Prince, Susan Staulcup, Stephen Medlin, Aaron J. Knox, Eric Y. Montgomery, V. J. Chen, Pavan Guttipatti, Callista Tran, Neil A. Feldstein, James M. Johnston, Michael C. Dewan, Toba N. Niazi, Eric M. Thompson, Laura M. Prolo, Eric M. Jackson, Kevin Ginn, Avery Wright, R. W. Dudley, Lindsay Kilburn, Joshua J. Chern, J. Leonard, Sandi Lam, David S. Hersh, Richard C. E. Anderson, Ross Mangum, Cassie Kline, Siddhartha S. Mitra, Todd C. Hankinson

Why this work is in the frame

A frame that forgets how it found something cannot be audited. These are the routes that admitted this work.

affAt least one author lists a Canadian institution in the pinned OpenAlex snapshot.

Bibliographic record

VenueNeuro-Oncology Pediatrics · 2025
Typearticle
Languageen
FieldMedicine
TopicPituitary Gland Disorders and Treatments
Canadian institutionsMontreal Children's Hospital
Fundersnot available
KeywordsCraniopharyngiomaProportional hazards modelDiseaseHormoneHazard ratioCancer

Abstract

fetched live from OpenAlex

Abstract Background Adamantinomatous craniopharyngioma (ACP) comprises 5-11% of pediatric intracranial tumors and is associated with poor quality of life. In general, cancer outcome studies indicate that females have higher survival rates and better treatment responses than males. Leading theories focus on sex-related genetic/molecular differences versus sex hormone differences as primary contributors to the different outcomes. Here, we investigated sex-associated differences in survival and functional outcomes of prepubescent patients with ACP, aiming to study the role of biological sex in the absence of hormonal effects. Methods Sixty-four patients diagnosed with ACP under 7 years of age were retrospectively identified from the Advancing Treatment for Pediatric Craniopharyngioma (ATPC) and the Children’s Hospital Colorado databases. A Cox regression model was used to evaluate time to recurrence/progression. A linear regression model was used to evaluate functional outcomes compared to pre-treatment baseline using a modified Craniopharyngioma Clinical Status Scale (CCSS). Patient age and length of follow-up were included as covariates. Results We found that sex is a statistically significant predictor of disease progression (p = 0.0183, power = 0.999), with males demonstrating a 57.4% lower risk of progression (95% CI [13.5%, 79.0%]). In contrast, patient age and follow-up duration did not significantly affect the hazard of progression. There was no statistically significant difference in neurological, visual, pituitary, or hypothalamic functional outcomes between males and females. Conclusions Our study finds that in prepubescent ACP patients, males have a lower risk of disease progression than females, although the functional outcomes are equivalent. With an underdeveloped hypothalamic-pituitary-­gonadal axis in prepubertal patients, the observed sex difference is likely attributed to factors such as genetic and molecular differences other than hormonal effects. This study highlights the need to identify variables impacting ACP disease course and advocates for personalized treatment strategies to improve patient outcomes and quality of life.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

Full frame distilled prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. Learned from the 10,348 direct Codex labels and 10,348 direct Gemma labels. Candidate is the union of thresholded teacher heads; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels or direct frontier model labels.

metaresearch head score (Codex)0.000
metaresearch head score (Gemma)0.000
Version: codex-gemma-dda1882f352aValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Observational · Consensus signal: Observational
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.008
Threshold uncertainty score0.502

Codex and Gemma teacher scores by category

CategoryCodexGemma
Metaresearch0.0000.000
Meta-epidemiology (narrow)0.0000.000
Meta-epidemiology (broad)0.0000.000
Bibliometrics0.0000.000
Science and technology studies0.0000.000
Scholarly communication0.0000.000
Open science0.0000.000
Research integrity0.0000.000
Insufficient payload (model declined to judge)0.0000.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.012
GPT teacher head0.272
Teacher spread0.260 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it