MétaCan
Menu
Back to cohort
Record W2803074059 · doi:10.1212/wnl.0000000000005660

Typical features of Parkinson disease and diagnostic challenges with microdeletion 22q11.2

2018· article· en· W2803074059 on OpenAlexafffund
Erik Boot, Nancy J. Butcher, Sean Udow, Connie Marras, Kin Y. Mok, Satoshi Kaneko, Matthew J. Barrett, Paolo Prontera, Brian D. Berman, Mario Masellis, Boris Dufournet, Karine Nguyen, Perrine Charles, Eugénie Mutez, Téodor Danaila, Aurélia Jacquette, Olivier Colin, Sophie Drapier, Michel Borg, Ania Fiksinski, Elfi Vergaelen, Ann Swillen, Annick Vogels, Annika Plate, Claudia Perandones, Thomas Gasser, Kristien Clerinx, Frédéric Bourdain, K.R. Mills, Nigel Williams, Nicholas Wood, Jan Booij, Anthony E. Lang, Anne S. Bassett, Nicola Tambasco, Gabriela M. Repetto, Rosemarie Fritsch, Barber M Tinselboer, Jacob Vorstman, Luis A. Pellene, Stephen G. Reich, Claudia Schulte

Bibliographic record

VenueNeurology · 2018
Typearticle
Languageen
FieldBiochemistry, Genetics and Molecular Biology
TopicCongenital heart defects research
Canadian institutionsCentre for Disability Prevention and Rehabilitation
FundersNational Institute of Mental HealthMedical Research CouncilCampbell Family Mental Health Research InstituteNational Institutes of HealthUniversity of TorontoHong Kong GovernmentInnovation and Technology CommissionFondation Brain CanadaParkinson's UKCanadian Institutes of Health ResearchNational Institute of Neurological Disorders and StrokeNational Institute for Health and Care ResearchSunnybrook FoundationDystonia CoalitionNational Center for Advancing Translational SciencesWellcome Trust
KeywordsMedicineDeletion syndromePediatricsAntipsychoticLevodopaDystoniaInternal medicineAnxietyComorbidityDiseaseAge of onsetPsychosisMoodNeuroimagingParkinson's diseasePsychiatrySchizophrenia (object-oriented programming)

Abstract

fetched live from OpenAlex

<h3>Objective</h3> To delineate the natural history, diagnosis, and treatment response of Parkinson disease (PD) in individuals with 22q11.2 deletion syndrome (22q11.2DS), and to determine if these patients differ from those with idiopathic PD. <h3>Methods</h3> In this international observational study, we characterized the clinical and neuroimaging features of 45 individuals with 22q11.2DS and PD (mean follow-up 7.5 ± 4.1 years). <h3>Results</h3> 22q11.2DS PD had a typical male excess (32 male, 71.1%), presentation and progression of hallmark motor symptoms, reduced striatal dopamine transporter binding with molecular imaging, and initial positive response to levodopa (93.3%). Mean age at motor symptom onset was relatively young (39.5 ± 8.5 years); 71.4% of cases had early-onset PD (&lt;45 years). Despite having a similar age at onset, the diagnosis of PD was delayed in patients with a history of antipsychotic treatment compared with antipsychotic-naive patients (median 5 vs 1 year, <i>p</i> = 0.001). Preexisting psychotic disorders (24.5%) and mood or anxiety disorders (31.1%) were common, as were early dystonia (19.4%) and a history of seizures (33.3%). <h3>Conclusions</h3> Major clinical characteristics and response to standard treatments appear comparable in 22q11.2DS-associated PD to those in idiopathic PD, although the average age at onset is earlier. Importantly, treatment of preexisting psychotic illness may delay diagnosis of PD in 22q11.DS patients. An index of suspicion and vigilance for complex comorbidity may assist in identifying patients to prioritize for genetic testing.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame distilled prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. Learned from the 10,348 direct Codex labels and 10,348 direct Gemma labels. Candidate is the union of thresholded teacher heads; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels or direct frontier model labels.

metaresearch head score (Codex)0.000
metaresearch head score (Gemma)0.000
Version: codex-gemma-dda1882f352aValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Observational · Consensus signal: none
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.773
Threshold uncertainty score0.254

Codex and Gemma teacher scores by category

CategoryCodexGemma
Metaresearch0.0000.000
Meta-epidemiology (narrow)0.0000.000
Meta-epidemiology (broad)0.0000.000
Bibliometrics0.0000.000
Science and technology studies0.0000.000
Scholarly communication0.0000.000
Open science0.0000.000
Research integrity0.0000.000
Insufficient payload (model declined to judge)0.0000.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.011
GPT teacher head0.256
Teacher spread0.245 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one teacher head, not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designObservational
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations45
Published2018
Admission routes2
Has abstractyes

Explore more

Same venueNeurologySame topicCongenital heart defects researchFrench-language works237,207