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Record W4214535941 · doi:10.22263/2312-4156.2021.6.118

BARTH’S SYNDROME: BRIEF REVIEW AND CLINICAL CASE

2021· article· en· W4214535941 on OpenAlexfundno aff
H.M. Biardouskaya, Н.В. Миклаш, H.I. Yakhimchyk, I.M. Motyuk

Bibliographic record

VenueVestnik of Vitebsk State Medical University · 2021
Typearticle
Languageen
FieldBiochemistry, Genetics and Molecular Biology
TopicMitochondrial Function and Pathology
Canadian institutionsnot available
FundersInstitute of GeneticsDirectorate for Biological SciencesNational Academy of Sciences of Belarus
KeywordsMedicineHeart failureInternal medicineCardiologyDigoxinDifferential diagnosisDiseaseContractilityHeart diseasePediatricsGastroenterologyEndocrinologyPathology

Abstract

fetched live from OpenAlex

The article describes a rare progressive disease of the cardiovascular system, hereditary mitochondrial pathology - Barth’s syndrome (3-methylglutacone aciduria type 2). A list of diseases for the differential diagnosis is given. A case of clinical observation of Barth’s syndrome is considered. In the presented case, the disease manifested itself at the age of up to one year and was characterized by the signs of heart failure, muscle hypotension, and a decrease in the number of neutrophils in the peripheral blood. The child was repeatedly observed in the hospital, received treatment with an inhibitor of an angio-converting enzyme, digoxin, acetylsalicylic acid, was consulted by a geneticist. A splicing mutation was revealed in the 3rd exon of the taphazin gene. The combination in the clinical picture of the signs of heart failure, muscle hypotension, protein-energy insufficiency, neutropenia, onset in the first year of life, a decrease in the contractility of the left ventricular myocardium, an increase in the size of the heart and a decrease in its contractility gave rise to suspicion of this disease. Barth’s syndrome was confirmed by genetic testing.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame distilled prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. Learned from the 10,348 direct Codex labels and 10,348 direct Gemma labels. Candidate is the union of thresholded teacher heads; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels or direct frontier model labels.

metaresearch head score (Codex)0.000
metaresearch head score (Gemma)0.001
Version: codex-gemma-dda1882f352aValidation status: machine_predicted_unvalidated
Candidate categoriesnone
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Not applicable · Consensus signal: none
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.636
Threshold uncertainty score0.508

Codex and Gemma teacher scores by category

CategoryCodexGemma
Metaresearch0.0000.001
Meta-epidemiology (narrow)0.0000.000
Meta-epidemiology (broad)0.0000.000
Bibliometrics0.0000.000
Science and technology studies0.0000.000
Scholarly communication0.0000.000
Open science0.0000.000
Research integrity0.0000.000
Insufficient payload (model declined to judge)0.0000.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.012
GPT teacher head0.269
Teacher spread0.257 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one teacher head, not a consensus.

The models applied no category: nothing in the taxonomy fit this work.
Study designNot applicable
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations0
Published2021
Admission routes1
Has abstractyes

Explore more

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