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Record W4403789330 · doi:10.1093/brain/awae349

Novel risk loci in LGI1-antibody encephalitis: genome-wide association study discovery and validation cohorts

2024· review· en· W4403789330 on OpenAlexfundno aff
Sophie Binks, Katherine S. Elliott, Sergio Muñiz‐Castrillo, Edmund Gilbert, Tânia Kawasaki de Araujo, Andrew R. Harper, Andrew Brown, Amanda Y. Chong, Gavin Band, Vicente Peris Sempere, Anne‐Laurie Pinto, Félicie Costantino, N. William Rayner, Alexander J. Mentzer, Norman Delanty, Véronique Rogemond, Géraldine Picard, Adam E. Handel, Nico Melzer, Maarten J. Titulaer, Soon‐Tae Lee, Frank Leypoldt, Gregor Kuhlenbäeumer, Jérôme Honnorat, Emmanuel Mignot, Gianpiero L Cavelleri, Julian C. Knight, Sarosh R. Irani

Bibliographic record

VenueBrain · 2024
Typereview
Languageen
FieldMedicine
TopicAutoimmune Neurological Disorders and Treatments
Canadian institutionsnot available
FundersWellcome TrustAgence Nationale de la RechercheNIHR Oxford Biomedical Research CentreBMA Foundation for Medical ResearchFundação de Amparo à Pesquisa do Estado de São PauloMedical Research Council CanadaNational Institute of Neurological Disorders and StrokeNational Institute for Health and Care ResearchBundesministerium für Bildung und ForschungBiomedical Research CouncilMedical Research CouncilWellcome
KeywordsGenome-wide association studyBiologyComputational biologyGeneticsSingle-nucleotide polymorphismGeneGenotype

Abstract

fetched live from OpenAlex

Encephalitis with antibodies to leucine-rich glioma-inactivated 1 (LGI1-Ab-E) is a common form of autoimmune encephalitis, presenting with seizures and neuropsychiatric changes, predominantly in older males. More than 90% of patients carry the human leukocyte antigen (HLA) class II allele, HLA-DRB1*07:01. However, this is also present in 25% of healthy controls. Therefore, we hypothesized the presence of additional genetic predispositions. In this genome-wide association study and meta-analysis, we studied a discovery cohort of 131 French LGI1-Ab-E and a validation cohort of 126 American, British and Irish LGI1-Ab-E patients, ancestry-matched to 2613 and 2538 European controls, respectively. Outside the known major HLA signal, we found two single nucleotide polymorphisms at genome-wide significance (P < 5 × 10-8), implicating PTPRD, a protein tyrosine phosphatase, and LINC00670, a non-protein coding RNA gene. Meta-analysis defined four additional non-HLA loci, including the protein coding COBL gene. Polygenic risk scores with and without HLA variants proposed a contribution of non-HLA loci. In silico network analyses suggested LGI1 and PTPRD-mediated interactions via the established receptors of LGI1, ADAM22 and ADAM23. Our results identify new genetic loci in LGI1-Ab-E. These findings present opportunities for mechanistic studies and offer potential markers of susceptibility, prognostics and therapeutic responses.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame distilled prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. Learned from the 10,348 direct Codex labels and 10,348 direct Gemma labels. Candidate is the union of thresholded teacher heads; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels or direct frontier model labels.

metaresearch head score (Codex)0.001
metaresearch head score (Gemma)0.001
Version: codex-gemma-dda1882f352aValidation status: machine_predicted_unvalidated
Candidate categoriesMeta-epidemiology (narrow)
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Observational · Consensus signal: Observational
GenreCandidate signal: Review · Consensus signal: Review
Teacher disagreement score0.464
Threshold uncertainty score1.000

Codex and Gemma teacher scores by category

CategoryCodexGemma
Metaresearch0.0010.001
Meta-epidemiology (narrow)0.0000.000
Meta-epidemiology (broad)0.0010.000
Bibliometrics0.0000.000
Science and technology studies0.0000.000
Scholarly communication0.0000.000
Open science0.0000.000
Research integrity0.0000.001
Insufficient payload (model declined to judge)0.0000.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.031
GPT teacher head0.344
Teacher spread0.314 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one teacher head, not a consensus.

Study designObservational
Domainnot available
GenreReview

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations9
Published2024
Admission routes1
Has abstractyes

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