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Record W4413139885 · doi:10.1093/brain/awaf259

Associations between epilepsy-related polygenic risk and brain morphology in childhood

2025· article· en· W4413139885 on OpenAlexafffund
Alexander Ngo, Lang Liu, Sara Larivière, Valeria Kebets, Serena Fett, Clara F. Weber, Eric Yu, Raúl Rodríguez‐Cruces, Zhiqiang Zhang, Leon Qi Rong Ooi, B.T. Thomas Yeo, Birgit Frauscher, Casey Paquola, Maria Eugenia Caligiuri, Antonio Gambardella, Luis Concha, Simon S. Keller, Fernando Cendes, Clarissa Lin Yasuda, Leonardo Bonilha, Ezequiel Gleichgerrcht, Niels K. Focke, Raviteja Kotikalapudi, Terence J. O’Brien, Lucy Vivash, Patricia Desmond, Elaine Lui, Anna Elisabetta Vaudano, Stefano Meletti, Reetta Kälviäinen, Hamid Soltanian‐Zadeh, Gavin P. Winston, Vijay Tiwari, Barbara A. K. Kreilkamp, Matteo Lenge, Renzo Guerrini, Khalid Hamandi, Theodor Rüber, Tobias Bauer, Orrin Devinsky, Erik Kaestner, Sean N. Hatton, Lorenzo Caciagli, Matthias Kirschner, John S. Duncan, Paul M. Thompson, Esmaeil Davoodi‐Bojd, Norman Delanty, Chantal Depondt, Colin P. Doherty, Martin Domín, Sonya Foley, Aoife Griffin, Graeme D. Jackson, Magdalena Kowalczyk, Angelo Labate, Sönke Langner, Mario Mascalchi, Pascal Martin, Mark P. Richardson, Christian Rummel, Mira Semmelroch, Mariasavina Severino, Aditi Singh, Rhys H. Thomas, Manuela Tondelli, Domenico Tortora, Felix von Podewills, Sjoerd B. Vos, Christopher D. Whelan, Roland Wiest, Junsong Zhang, Carrie R. McDonald, Sanjay M. Sisodiya, Neda Bernasconi, Andrea Bernasconi, Ziv Gan‐Or, Boris C. Bernhardt

Bibliographic record

VenueBrain · 2025
Typearticle
Languageen
FieldNeuroscience
TopicFunctional Brain Connectivity Studies
Canadian institutionsCentre Hospitalier Universitaire de SherbrookeQueen's UniversityUniversité de SherbrookeMcGill UniversityMcGill Genome CentreMontreal Neurological Institute and Hospital
FundersEpilepsy CanadaNational Institute of Neurological Disorders and StrokeNational Medical Research CouncilNational Center for Advancing Translational SciencesMontreal Neurological Institute and HospitalEpilepsy SocietyMedical Research CouncilNational Institutes of HealthCanadian Institutes of Health ResearchTemasek FoundationHealth and Care Research WalesFonds de Recherche du Québec - SantéCentro Singular de Investigación de GaliciaSick Kids FoundationMedical Research CentreSaastamoisen säätiöNational Science FoundationChina Postdoctoral Science FoundationConsejo Nacional de Ciencia y Tecnología, ParaguayNorges IdrettshøgskoleMedizinische Fakultät, Rheinische Friedrich-Wilhelms-Universität BonnXuzhou Medical UniversityCentre Azrieli de recherche sur l'autisme, Institut et Hôpital Neurologiques de MontréalUniversity College London Hospitals NHS Foundation TrustCanadian Open Neuroscience PlatformNational Center for Geriatrics and GerontologyDirección General de Asuntos del Personal Académico, Universidad Nacional Autónoma de MéxicoConsejo Nacional de Ciencia y TecnologíaCanada Research ChairsConselho Nacional de Desenvolvimento Científico e TecnológicoNational Natural Science Foundation of ChinaMichael J. Fox Foundation for Parkinson's ResearchNational Health and Medical Research CouncilEuropean CommissionFundação de Amparo à Pesquisa do Estado de São PauloDeutsche ForschungsgemeinschaftFondation Brain CanadaMinistry of Health -SingaporeNational University of SingaporeUniversité de SherbrookeUniversity College LondonNatural Sciences and Engineering Research Council of CanadaBundesministerium für Bildung und ForschungNational Institute for Health and Care ResearchConsortium canadien en neurodégénérescence associée au vieillissementMinistero della SaluteAustralian GovernmentGalen and Hilary Weston Foundation
KeywordsNeurotypicalEpilepsyTemporal lobeNeuroimagingAtrophyHippocampal sclerosisBrain morphometryNeurosciencePopulationGenetic architecturePsychologyEpilepsy syndromesMagnetic resonance imagingMedicinePathologyAutismQuantitative trait locusDevelopmental psychologyAutism spectrum disorder

Abstract

fetched live from OpenAlex

Extensive neuroimaging research in temporal lobe epilepsy with hippocampal sclerosis (TLE-HS) has identified brain atrophy as a disease phenotype. While it is also related to a complex genetic architecture, the transition from genetic risk factors to brain vulnerabilities remains unclear. Using a population-based approach, we examined the associations between epilepsy-related polygenic risk for HS (PRS-HS) and brain structure in healthy developing children, assessed their relation to brain network architecture, and evaluated its correspondence with case-control findings in TLE-HS diagnosed patients relative to healthy individuals. We used genome-wide genotyping and structural T1-weighted MRI of 3826 neurotypical children from the Adolescent Brain Cognitive Development (ABCD) study. Surface-based linear models related PRS-HS to cortical thickness measures, and subsequently contextualized findings with structural and functional network architecture based on epicentre mapping approaches. Imaging-genetic associations were then correlated to atrophy and disease epicentres in 785 patients with TLE-HS relative to 1512 healthy controls aggregated across multiple sites. Higher PRS-HS was associated with decreases in cortical thickness across temporo-parietal as well as fronto-central regions of neurotypical children. These imaging-genetic effects were anchored to the connectivity profiles of distinct functional and structural epicentres. Compared with disease-related alterations from a separate epilepsy cohort, regional and network correlates of PRS-HS strongly mirrored cortical atrophy and disease epicentres observed in patients with TLE-HS and were highly replicable across different studies. Findings were consistent when using statistical models controlling for spatial autocorrelations and robust to variations in analytic methods. Capitalizing on recent imaging-genetic initiatives, our study provides novel insights into the genetic underpinnings of structural alterations in TLE-HS, revealing common morphological and network pathways between genetic vulnerability and disease mechanisms. These signatures offer a foundation for early risk stratification and personalized interventions targeting genetic profiles in epilepsy.

Fetched live from OpenAlex and de-inverted. Abstracts are not stored in this database: the inverted indexes are 8.6 GB of the frame’s 9.3 GB of text, and the host has 13 GB free.

How this classification was reachedexpand

Full frame distilled prediction

Teacher imitation

Not calibrated prevalence, not ground truth. Human validation pending. Learned from the 10,348 direct Codex labels and 10,348 direct Gemma labels. Candidate is the union of thresholded teacher heads; consensus is their intersection. These outputs are machine_predicted_unvalidated and are not human labels or direct frontier model labels.

metaresearch head score (Codex)0.001
metaresearch head score (Gemma)0.041
Version: codex-gemma-dda1882f352aValidation status: machine_predicted_unvalidated
Candidate categoriesMetaresearch
Consensus categoriesnone
DomainCandidate signal: none · Consensus signal: none
Study designCandidate signal: Observational · Consensus signal: Observational
GenreCandidate signal: Empirical · Consensus signal: Empirical
Teacher disagreement score0.071
Threshold uncertainty score0.967

Codex and Gemma teacher scores by category

CategoryCodexGemma
Metaresearch0.0010.041
Meta-epidemiology (narrow)0.0000.000
Meta-epidemiology (broad)0.0000.000
Bibliometrics0.0000.001
Science and technology studies0.0000.000
Scholarly communication0.0000.000
Open science0.0000.000
Research integrity0.0000.000
Insufficient payload (model declined to judge)0.0000.000

Machine scores (provisional)

The two teacher heads of the student model, read on this work. A score orders the frame for review; it never asserts a category, and the validation status ships verbatim with every row.

Baseline scores from an immature model (maturity gate not passed, 7 training rounds). Scores rank; they never assert a category.

Opus teacher head0.016
GPT teacher head0.265
Teacher spread0.249 · how far apart the two teachers sit on this one work
Validation statusscore_only:v0-immature-baseline · verbatim from the scoring run: score_only means the number may rank works, and no category label ships from it

Classification

machine, unvalidated

Machine predicted; a candidate call from one teacher head, not a consensus.

Study designObservational
Domainnot available
GenreEmpirical

How this classification was reached, model by model and score by score, is at the end of the page under "How this classification was reached".

Quick stats

Citations3
Published2025
Admission routes2
Has abstractyes

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